Back to Search
Start Over
Skeletal abnormalities, pediatric-onset severe osteoporosis, and multiple fragility fractures in a patient with a novel CTNNB1 de novo variant
- Source :
- Bone Reports, Vol 21, Iss , Pp 101777- (2024)
- Publication Year :
- 2024
- Publisher :
- Elsevier, 2024.
-
Abstract
- We report a case of a patient with a de novo germline heterozygous truncating variant of CTNNB1 gene (c.2172del, p.Tyr724Ter) causing neurodevelopmental disorder with spastic diplegia and visual defects syndrome (NEDSDV) associated with a new clinical feature — severe pediatric-onset osteoporosis and multiple fractures. A functional effect of the identified variant was demonstrated using adipose-tissue derived primary mesenchymal stem cells, where we detected the alteration of CTNNB1mRNA and β-catenin protein levels using real-time PCR and Western blot analysis.
Details
- Language :
- English
- ISSN :
- 23521872
- Volume :
- 21
- Issue :
- 101777-
- Database :
- Directory of Open Access Journals
- Journal :
- Bone Reports
- Publication Type :
- Academic Journal
- Accession number :
- edsdoj.0d254560ddb448c189ae537ba88345dc
- Document Type :
- article
- Full Text :
- https://doi.org/10.1016/j.bonr.2024.101777