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Next generation sequencing for diagnosis of hereditary anemia: Experience in a Spanish reference center

Authors :
Jorge M. Nieto
Sara Rochas-López
Fernando A. González-Fernández
Ana Villegas-Martínez
Estefanía Bolaños-Calderón
Eduardo Salido-Fiérrez
Elena Cela
Jorge Huerta-Aragoneses
María Ordoñez-García
María J. Muruzábal-Sitges
Mariola Abio-Calvete
Julián Sevilla Navarro
Silvia de la Iglesia
Marta Morado
Sonsoles San Román-Pacheco
María L. Martín-Mateos
María V. Recasens-Flores
Celina Benavente-Cuesta
Paloma Ropero-Gradilla
null Members of the erithropatology working group
Source :
Clinica chimica acta; international journal of clinical chemistry. 531
Publication Year :
2022

Abstract

Hereditary anemia (HA) encloses a wide group of rare inherited disorders with clinical and hematologic overlaps that complicate diagnosis.A 48-gene panel was developed to diagnose HA by Next Generation Sequencing (NGS) in a large cohort of 165 patients from 160 unrelated families.Patients were divided in: A) patients who had a suspicion of a specific type of HA (n = 109), and B) patients who had a suspicion of HA but with no clear type (n = 56). Diagnostic performance was 83.5% in group A and a change of the initial diagnosis occurred in 11% of these patients. In group B, 35.7% of patients achieved a genetic diagnosis. NGS identified 6 cases of xerocytosis, 6 of pyruvate kinase (PK) deficiency, 4 of G6PD, and 1 case of phytosterolemia with no initial suspicion of these pathologies, which is clinically relevant since they have specific treatment. Five patients were found to carry variants associated to two different pathologies (4 of them combining a metabolic deficiency and a membrane defect), and 44 new variants were identified in 41 patients.The use of NGS is a sensitive technique to diagnose HA and it shows better performance when patients are better characterized.

Details

ISSN :
18733492
Volume :
531
Database :
OpenAIRE
Journal :
Clinica chimica acta; international journal of clinical chemistry
Accession number :
edsair.doi.dedup.....73db9ebc6d7f89cad5650daab57a8789