An unusual case of unicystic ameloblastoma showing typical clinical findings of dentigerous cyst

We describe a case of unicystic ameloblastoma in the left lower wisdom tooth region in a 16-year-old girl. Clinical examinations showed typical features of a dentigerous cyst. Although a lining epithelium was observed in the unicystic lesion, tumor nests characteristic of an enamel organ were also present as lining epithelial elements, and island-like and mass-like regions of ameloblastoma were found in the connective tissue of the cystic wall. Small amounts of calcified materials were noted in the tumor nests. These findings suggested that this case was an unusual unicystic ameloblastoma derived from the epithelium lining a follicular detal cyst.