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High risk of malignancy in mosaic variegated aneuploidy syndrome

Authors :
Jean Marie Rival
Francoise Mechinaud
Sébastien Jacquemont
Michelle Boceno
Albert David
Source :
American Journal of Medical Genetics. 109:17-21
Publication Year :
2002
Publisher :
Wiley, 2002.

Abstract

Fourteen cases of mosaic variegated aneuploidy (MVA) syndrome have been reported in the last 10 years. The phenotype of this rare condition has been quite consistent: severe microcephaly, growth deficiency, mild physical anomalies, and mental retardation. We describe here a young boy in whom MVA syndrome is associated to myelodysplasia with a monosomy 7 bone marrow clone. At the age of 3 years, myelodysplasia progressed to an acute lymphoblastic leukemia, and the patient died soon after. Several syndromes with short stature and severe microcephaly, such as the Seckel and Nijmegen syndromes, comprise hematological findings and chromosome instability. However, chromosome instability was not confirmed in our patient. MVA with hematological findings has not been reported before, but 3 patients of 14 (21%) have developed a malignancy (rhabdomyosarcoma, acute lymphoblastic leukemia, and nephroblastoma). Therefore, we propose that MVA is a condition predisposing to neoplasia.

Details

ISSN :
01487299
Volume :
109
Database :
OpenAIRE
Journal :
American Journal of Medical Genetics
Accession number :
edsair.doi...........792c484ddb18992863a91a8fb270c40c
Full Text :
https://doi.org/10.1002/ajmg.10281