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Increased frequency of repeat expansion mutations across different populations

Authors :
Ibañez, Kristina
Jadhav, Bharati
Zanovello, Matteo
Gagliardi, Delia
Clarkson, Christopher
Facchini, Stefano
Garg, Paras
Martin-Trujillo, Alejandro
Gies, Scott J.
Galassi Deforie, Valentina
Dalmia, Anupriya
Hensman Moss, Davina J.
Vandrovcova, Jana
Rocca, Clarissa
Moutsianas, Loukas
Marini-Bettolo, Chiara
Walker, Helen
Turner, Chris
Shoai, Maryam
Long, Jeffrey D.
Fratta, Pietro
Langbehn, Douglas R.
Tabrizi, Sarah J.
Caulfield, Mark J.
Cortese, Andrea
Escott-Price, Valentina
Hardy, John
Houlden, Henry
Sharp, Andrew J.
Tucci, Arianna
Source :
Nature Medicine; November 2024, Vol. 30 Issue: 11 p3357-3368, 12p
Publication Year :
2024

Abstract

Repeat expansion disorders (REDs) are a devastating group of predominantly neurological diseases. Together they are common, affecting 1 in 3,000 people worldwide with population-specific differences. However, prevalence estimates of REDs are hampered by heterogeneous clinical presentation, variable geographic distributions and technological limitations leading to underascertainment. Here, leveraging whole-genome sequencing data from 82,176 individuals from different populations, we found an overall disease allele frequency of REDs of 1 in 283 individuals. Modeling disease prevalence using genetic data, age at onset and survival, we show that the expected number of people with REDs would be two to three times higher than currently reported figures, indicating underdiagnosis and/or incomplete penetrance. While some REDs are population specific, for example, Huntington disease-like 2 in Africans, most REDs are represented in all broad genetic ancestries (that is, Europeans, Africans, Americans, East Asians and South Asians), challenging the notion that some REDs are found only in specific populations. These results have worldwide implications for local and global health communities in the diagnosis and counseling of REDs.

Details

Language :
English
ISSN :
10788956 and 1546170X
Volume :
30
Issue :
11
Database :
Supplemental Index
Journal :
Nature Medicine
Publication Type :
Periodical
Accession number :
ejs67586060
Full Text :
https://doi.org/10.1038/s41591-024-03190-5