Back to Search Start Over

Unusual non-nanophthalmic uveal effusion syndrome with histologically normal scleral architecture: a case report.

Authors :
Kaewsangthong, Kasama
Thoongsuwan, Somanus
Uiprasertkul, Mongkol
Phasukkijwatana, Nopasak
Source :
BMC Ophthalmology; 7/29/2020, Vol. 20 Issue 1, p1-6, 6p
Publication Year :
2020

Abstract

<bold>Background: </bold>To report an unusual case of non-nanophthalmic uveal effusion syndrome (UES) with histologically normal sclera but responsive to scleral resection.<bold>Case Presentation: </bold>A73-year-old man presented with a bullous retinal detachment without ciliochoroidal detachment on funduscopic examination of the right eye. The axial length of both eyes was normal. Extensive investigations for possible causes of exudative retinal detachment were performed with unremarkable results except for choroidal hyperpermeability on indocyanine green angiography (ICGA). Ultrasound biomicroscopy (UBM) revealed scleral thickening with peripheral choroidal elevation leading to the diagnosis of UES. Partial thickness sclerectomy and sclerotomy was performed resulting in complete retinal reattachment, reduction of choroidal hyperpermeability on ICGA and improvement of visual acuity. However, histological studies of the excised sclera revealed no scleral architectural changes or abnormal deposits.<bold>Conclusions: </bold>The diagnosis of UES in non-nanophthalmic eyes is challenging. Thorough systemic and ocular investigations are critical to rule out other etiologies. UBM can be helpful to evaluate scleral thickness and anterior choroid in equivocal cases. Our case was unique in that, although the sclera was thick, no abnormal microscopic scleral architecture could be identified. Misdiagnosis may lead to different surgical procedures such as vitrectomy resulting in unfavorable outcomes. [ABSTRACT FROM AUTHOR]

Details

Language :
English
ISSN :
14712415
Volume :
20
Issue :
1
Database :
Complementary Index
Journal :
BMC Ophthalmology
Publication Type :
Academic Journal
Accession number :
144825095
Full Text :
https://doi.org/10.1186/s12886-020-01581-z