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Occipital horn syndrome and a mild Menkes phenotype associated with splice site mutations at the MNK locus.

Authors :
Kaler SG
Gallo LK
Proud VK
Percy AK
Mark Y
Segal NA
Goldstein DS
Holmes CS
Gahl WA
Source :
Nature genetics [Nat Genet] 1994 Oct; Vol. 8 (2), pp. 195-202.
Publication Year :
1994

Abstract

We have found mutations in the Menkes disease gene (MNK) which impair, but do not abolish, correct mRNA splicing in patients with less severe clinical phenotypes. In one family, four males aged 2-36 years with a distinctive Menkes variant have a mutation at the +3 position of a splice donor site near the 3' end of the Menkes coding sequence that is associated with exon skipping and a stable mutant transcript. In an unrelated 15-year-old male with typical occipital horn syndrome, a point mutation at the -2 exonic position of a splice donor site in the middle of the gene causes exon-skipping and activation of a cryptic splice acceptor site. In both mutations, maintenance of some normal splicing is demonstrable by RT-PCR, cDNA sequencing and ribonuclease protection.

Details

Language :
English
ISSN :
1061-4036
Volume :
8
Issue :
2
Database :
MEDLINE
Journal :
Nature genetics
Publication Type :
Academic Journal
Accession number :
7842019
Full Text :
https://doi.org/10.1038/ng1094-195