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Birt-Hogg-Dubé syndrome - an unique case series.

Authors :
Thakare PH
Utpat K
Desai U
Joshi J
Nayak C
Source :
Advances in respiratory medicine [Adv Respir Med] 2021; Vol. 89 (1), pp. 55-59. Date of Electronic Publication: 2021 Jan 20.
Publication Year :
2021

Abstract

Birt-Hogg-Dubé syndrome (BHDS) is an uncommon autosomal dominant syndrome. It is also known as Hornstein-Knickenberg syndrome. It is an inherited disorder culminating in mutations in folliculin coding gene (FLCN). The clinical exhibitions of the syn-drome are multi-systemic, comprising of a constellation of pulmonary, dermatologic and renal system manifestations. The most common presentations include fibrofolliculomas, renal cell carcinomas, lung cysts and spontaneous pneumothorax. The treatment is conservative with regular monitoring of the renal and lung parameters. Fibrofolliculomas may require surgical excision and recurrent events of pneumothorax may warrant pleurodesis. We reported a case series of 2 patients presenting with symptoms of progressive breathlessness along with dermatological manifestations and subsequently showing radiological manifestations of Birt-Hogg-Dubé syndrome in the form of lung cysts.

Details

Language :
English
ISSN :
2543-6031
Volume :
89
Issue :
1
Database :
MEDLINE
Journal :
Advances in respiratory medicine
Publication Type :
Academic Journal
Accession number :
33471358
Full Text :
https://doi.org/10.5603/ARM.a2020.0180