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Genetic Testing Confirmed the Early Diagnosis of X-Linked Hypophosphatemic Rickets in a 7-Month-Old Infant.

Authors :
Poon KS
Sng AA
Ho CW
Koay ES
Loke KY
Source :
Journal of investigative medicine high impact case reports [J Investig Med High Impact Case Rep] 2015 Aug 03; Vol. 3 (3), pp. 2324709615598167. Date of Electronic Publication: 2015 Aug 03 (Print Publication: 2015).
Publication Year :
2015

Abstract

Loss-of-function mutations in the phosphate regulating gene with homologies to endopeptidases on the X-chromosome (PHEX) have been causally associated with X-linked hypophosphatemic rickets (XLHR). The early diagnosis of XLHR in infants is challenging when it is based solely on clinical features and biochemical findings. We report a 7-month-old boy with a family history of hypophosphatemic rickets., who demonstrated early clinical evidence of rickets, although serial biochemical findings could not definitively confirm rickets. A sequencing assay targeting the PHEX gene was first performed on the mother's DNA to screen for mutations in the 5'UTR, 22 coding exons, and the exon-intron junctions. Targeted mutation analysis and mRNA studies were subsequently performed on the boys' DNA to investigate the pathogenicity of the identified mutation. Genetic screening of the PHEX gene revealed a novel mutation, c.1080-2A>C, at the splice acceptor site in intron 9. The detection of an aberrant mRNA transcript with skipped (loss of) exon 10 establishes its pathogenicity and confirms the diagnosis of XLHR in this infant. Genetic testing of the PHEX gene resulted in early diagnosis of XLHR, thus enabling initiation of therapy and prevention of progressive rachitic changes in the infant.

Details

Language :
English
ISSN :
2324-7096
Volume :
3
Issue :
3
Database :
MEDLINE
Journal :
Journal of investigative medicine high impact case reports
Publication Type :
Academic Journal
Accession number :
26904698
Full Text :
https://doi.org/10.1177/2324709615598167