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Heterozygous inactivation of the Nf1 gene in myeloid cells enhances neointima formation via a rosuvastatin-sensitive cellular pathway.
- Source :
-
Human molecular genetics [Hum Mol Genet] 2013 Mar 01; Vol. 22 (5), pp. 977-88. Date of Electronic Publication: 2012 Nov 29. - Publication Year :
- 2013
-
Abstract
- Mutations in the NF1 tumor suppressor gene cause Neurofibromatosis type 1 (NF1). Neurofibromin, the protein product of NF1, functions as a negative regulator of Ras activity. Some NF1 patients develop cardiovascular disease, which represents an underrecognized disease complication and contributes to excess morbidity and mortality. Specifically, NF1 patients develop arterial occlusion resulting in tissue ischemia and sudden death. Murine studies demonstrate that heterozygous inactivation of Nf1 (Nf1(+/-)) in bone marrow cells enhances neointima formation following arterial injury. Macrophages infiltrate Nf1(+/-) neointimas, and NF1 patients have increased circulating inflammatory monocytes in their peripheral blood. Therefore, we tested the hypothesis that heterozygous inactivation of Nf1 in myeloid cells is sufficient for neointima formation. Specific ablation of a single copy of the Nf1 gene in myeloid cells alone mobilizes a discrete pro-inflammatory murine monocyte population via a cell autonomous and gene-dosage dependent mechanism. Furthermore, lineage-restricted heterozygous inactivation of Nf1 in myeloid cells is sufficient to reproduce the enhanced neointima formation observed in Nf1(+/-) mice when compared with wild-type controls, and homozygous inactivation of Nf1 in myeloid cells amplified the degree of arterial stenosis after arterial injury. Treatment of Nf1(+/-) mice with rosuvastatin, a stain with anti-inflammatory properties, significantly reduced neointima formation when compared with control. These studies identify neurofibromin-deficient myeloid cells as critical cellular effectors of Nf1(+/-) neointima formation and propose a potential therapeutic for NF1 cardiovascular disease.
- Subjects :
- Animals
Anti-Inflammatory Agents administration & dosage
Arterial Occlusive Diseases complications
Arterial Occlusive Diseases physiopathology
Bone Marrow Cells drug effects
Bone Marrow Cells metabolism
Heterozygote
Humans
Macrophages cytology
Macrophages pathology
Metabolic Networks and Pathways drug effects
Mice
Myeloid Cells cytology
Myeloid Cells drug effects
Myeloid Cells metabolism
Neointima physiopathology
Neurofibromatosis 1 complications
Neurofibromatosis 1 physiopathology
Neurofibromin 1 metabolism
Rosuvastatin Calcium
Arterial Occlusive Diseases genetics
Fluorobenzenes administration & dosage
Neointima drug therapy
Neointima genetics
Neurofibromatosis 1 genetics
Neurofibromin 1 genetics
Pyrimidines administration & dosage
Sulfonamides administration & dosage
Subjects
Details
- Language :
- English
- ISSN :
- 1460-2083
- Volume :
- 22
- Issue :
- 5
- Database :
- MEDLINE
- Journal :
- Human molecular genetics
- Publication Type :
- Academic Journal
- Accession number :
- 23197650
- Full Text :
- https://doi.org/10.1093/hmg/dds502