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Macrocephaly-capillary malformation syndrome in a newborn with tetralogy of fallot and sagittal sinus thrombosis.

Authors :
Ercan TE
Oztunc F
Celkan T
Bor M
Kizilkilic O
Vural M
Perk Y
Islak C
Tuysuz B
Source :
Journal of child neurology [J Child Neurol] 2013 Jan; Vol. 28 (1), pp. 115-9. Date of Electronic Publication: 2012 Mar 25.
Publication Year :
2013

Abstract

Macrocephaly-capillary malformation syndrome is characterized by cutaneous vascular malformations with associated anomalies as macrocephaly, macrosomia, hemihypertrophy, hypotonia, developmental delay, lax joints, loose skin, polysyndactyly, and neuroimaging abnormalities. We present a newborn with a prenatal diagnosis of macrosomia and tetralogy of Fallot. He also had macrocephaly; a high forehead; capillary hemangioma on the forehead, upper lip, and philtrum; generalized loose skin; postaxial polydactyly of both hands and feet, with neuroimaging findings of polymicrogyria and thrombosis in sagittal sinus and sinus rectus. His condition was diagnosed as macrocephaly-capillary malformation syndrome in the neonatal period and he died suddenly during sleep at 6 months of age. The clinical course in this syndrome is not as benign as was previously thought. Careful follow-up of these patients with particular emphasis on neuroradiologic and cardiologic evaluation might help decrease the risk of sudden death and to improve long-term outcome.

Details

Language :
English
ISSN :
1708-8283
Volume :
28
Issue :
1
Database :
MEDLINE
Journal :
Journal of child neurology
Publication Type :
Academic Journal
Accession number :
22451530
Full Text :
https://doi.org/10.1177/0883073812439346