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A case of IgG4-related sclerosing disease complicated by sclerosing cholangitis, retroperitoneal fibrosis and orbital pseudotumour.

Authors :
Nagai K
Hosaka H
Takahashi Y
Kubo S
Nakamura N
Andou K
Source :
BMJ case reports [BMJ Case Rep] 2009; Vol. 2009. Date of Electronic Publication: 2009 Jun 01.
Publication Year :
2009

Abstract

We present a case of IgG4-related sclerosing disease complicated by sclerosing cholangitis (SC), idiopathic retroperitoneal fibrosis (IRF) and orbital pseudotumour (OPT). Clinical, radiographic and pathological findings later suggested that the patient had SC complicated by IRF. The patient's SC and IRF were well controlled for the first 10 years of the follow-up period; OPT developed in the tenth year. During investigation of the OPT, serum IgG4 level was found to be significantly elevated. The patient was then diagnosed with IgG4-related sclerosing disease complicated by SC, IRF and OPT. This is a rare manifestation of IgG4-related sclerosing disease, which was diagnosed incidentally during OPT work-up. We suggest that this is a variation of the so-called IgG4-related sclerosing disease or hyper-IgG4 disease.

Details

Language :
English
ISSN :
1757-790X
Volume :
2009
Database :
MEDLINE
Journal :
BMJ case reports
Publication Type :
Academic Journal
Accession number :
21686984
Full Text :
https://doi.org/10.1136/bcr.02.2009.1590