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A new phenotype of dysferlinopathy with congenital onset.

Authors :
Paradas C
González-Quereda L
De Luna N
Gallardo E
García-Consuegra I
Gómez H
Cabello A
Illa I
Gallano P
Source :
Neuromuscular disorders : NMD [Neuromuscul Disord] 2009 Jan; Vol. 19 (1), pp. 21-5. Date of Electronic Publication: 2008 Dec 11.
Publication Year :
2009

Abstract

We report two patients with a new phenotype of dysferlinopathy presenting as congenital muscular disease. Both patients showed weakness in proximal lower limbs and neck flexor muscles at birth. The presence of normal CK levels during the first years should be noted. Initial MRI showed no abnormalities but short-time-inversion-recovery (STIR) sequences revealed a striking myoedema in gastrocnemius and hamstring muscles at the age of 5. Muscle biopsy showed mild dystrophic features and the absence of dysferlin. Dysferlin gene (DYSF) analysis revealed a p.Ala927LeufsX21 mutation in a homozygous state in both siblings. This new phenotype widens the clinical spectrum of dysferlin myopathies.

Details

Language :
English
ISSN :
0960-8966
Volume :
19
Issue :
1
Database :
MEDLINE
Journal :
Neuromuscular disorders : NMD
Publication Type :
Academic Journal
Accession number :
19084402
Full Text :
https://doi.org/10.1016/j.nmd.2008.09.015