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Serum prolactin as a tool for the follow-up of treated DHPR-deficient patients.
- Source :
-
Journal of inherited metabolic disease [J Inherit Metab Dis] 2008 Dec; Vol. 31 Suppl 2, pp. S193-7. Date of Electronic Publication: 2008 Apr 15. - Publication Year :
- 2008
-
Abstract
- Deficiency of dihydropteridine reductase causes a variant form of phenylketonuria associated with a devastating neurological disease characterized by mental retardation, hypokinesis and other features relating to basal ganglia disorder. Hyperphenylalaninaemias with tetrahydrobiopterin deficiency make up about 1-3% of all hyperphenylalaninaemias. We describe three patients from Calabria, a southern region of Italy, who have a dihydropteridine reductase deficiency, caused by the same mutation (p.L14P) also found in the nearby region of Sicily. We report the evolution of clinical and biochemical data during the treatment of these patients where we used prolactin serum determination to adapt the specific therapy. This report suggests that serum prolactin levels can be a good biomarker for optimal dosage of hydroxylated precursors in long-term treatment monitoring.
- Subjects :
- 5-Hydroxytryptophan administration & dosage
Aromatic Amino Acid Decarboxylase Inhibitors
Biomarkers blood
Carbidopa administration & dosage
Child, Preschool
Dietary Proteins administration & dosage
Dihydropteridine Reductase blood
Dopa Decarboxylase metabolism
Drug Therapy, Combination
Enzyme Inhibitors administration & dosage
Genetic Predisposition to Disease
Humans
Infant
Infant, Newborn
Italy
Levodopa administration & dosage
Monoamine Oxidase Inhibitors administration & dosage
Mutation
Neonatal Screening
Neurologic Examination
Phenotype
Phenylketonurias blood
Phenylketonurias diagnosis
Phenylketonurias genetics
Selegiline administration & dosage
Time Factors
Treatment Outcome
Dihydropteridine Reductase genetics
Dopamine Agents administration & dosage
Drug Monitoring methods
Phenylketonurias therapy
Prolactin blood
Subjects
Details
- Language :
- English
- ISSN :
- 1573-2665
- Volume :
- 31 Suppl 2
- Database :
- MEDLINE
- Journal :
- Journal of inherited metabolic disease
- Publication Type :
- Academic Journal
- Accession number :
- 18425437
- Full Text :
- https://doi.org/10.1007/s10545-007-0788-3