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Multiple intracranial aneurysms associated with branchio-oto-dysplasia.
- Source :
-
Journal of Korean medical science [J Korean Med Sci] 2001 Apr; Vol. 16 (2), pp. 245-9. - Publication Year :
- 2001
-
Abstract
- Branchio-oto-dysplasia is characterized by abnormalities of embryonic branchial arch system and deafness inherited as autosomal dominant with variable gene expression. We present a rare case of multiple intracranial aneurysms associated with branchio-oto-dysplasia. A 40-yr-old man with severe headache presented as spontaneous subarachnoid hemorrhage on brain computed tomographic scan. The patient also manifested clinical features of branchio-oto-dysplasia and right hemifacial hypoplasia. Carotid angiogram confirmed an aneurysm in the anterior communicating artery. Intraoperative findings demonstrated multiple aneurysms in the anterior communicating artery and in the left posterior communicating artery, which were clipped successfully. Postoperative course was uneventful. This condition has not been reported previously. We also reviewed literatures to discuss whether the intracranial aneurysm was as a coincidental finding or a part of this malformation.
- Subjects :
- Adult
Cerebral Angiography
Humans
Intracranial Aneurysm diagnostic imaging
Subarachnoid Hemorrhage diagnostic imaging
Subarachnoid Hemorrhage etiology
Temporal Bone abnormalities
Tomography, X-Ray Computed
Zygoma abnormalities
Branchio-Oto-Renal Syndrome complications
Intracranial Aneurysm etiology
Subjects
Details
- Language :
- English
- ISSN :
- 1011-8934
- Volume :
- 16
- Issue :
- 2
- Database :
- MEDLINE
- Journal :
- Journal of Korean medical science
- Publication Type :
- Academic Journal
- Accession number :
- 11306757
- Full Text :
- https://doi.org/10.3346/jkms.2001.16.2.245